CASE REPORT article

Front. Oncol., 15 January 2025

Sec. Thoracic Oncology

Volume 14 - 2024 | https://doi.org/10.3389/fonc.2024.1523104

Case report: A rare case of chondrosarcoma-like malignant giant cell tumor in adolescent rib: diagnostic challenges and treatment

  • 1. The Second Clinical Medical College, Lanzhou University, Lanzhou, China

  • 2. Department of Thoracic Surgery, Lanzhou University Second Hospital, Lanzhou, Gansu, China

Abstract

Chondrosarcoma-like malignant giant cell tumor (GCT) of the rib is an extremely rare and aggressive tumor, particularly in adolescents. This case report describes a 19-year-old female presenting with a GCT of the rib with chondrosarcomatous differentiation, highlighting the challenges posed by its unusual location and pathological complexity. Multidisciplinary diagnostic approaches, including advanced imaging, immunohistochemistry (IHC), and pathology, were essential for confirming the diagnosis. Key IHC markers such as Vimentin, SMA, and CD163, alongside genetic analysis excluding H3F3A mutations, guided the diagnostic process. The patient underwent successful surgical resection, achieving early recovery without adjuvant therapy. This report underscores the importance of early detection, precise pathological evaluation, and individualized surgical treatment for rare and high-risk tumors, emphasizing the need for long-term follow-up to monitor recurrence.

1 Introduction

Primary malignant bone tumors of the rib are extremely rare in clinical practice, especially among adolescents, with limited cases reported in the literature (1). Giant cell tumor (GCT) typically arise in the epiphyseal regions of long bones, such as the distal femur, proximal tibia, and distal radius, predominantly affecting individuals aged 20 to 40 (2). Although these long bones are typical sites of GCT occurrence, GCT in the rib is exceptionally rare (3). According to the WHO Classification of Tumors in Soft Tissue and Bone (5th edition, 2020), chondrosarcomatous differentiation in GCTs represents a distinct pathological entity with unique clinical and prognostic implications (4). Rib GCTs in adolescents are even more uncommon, often presenting as localized pain and swelling—symptoms that are easily misdiagnosed as benign conditions, such as costochondritis, rib fractures, or other non-specific inflammations (5).

These atypical presentations require clinicians to maintain high vigilance during the diagnostic process, with comprehensive imaging evaluations to exclude potential malignancies (6). In rare cases where GCTs show chondrosarcomatous differentiation, diagnosis and treatment become even more complex (7). This differentiation suggests a higher potential for malignancy and aggressiveness, possibly accompanied by a greater risk of recurrence (8). Such cases are rarely documented, particularly among adolescents with rib involvement.

Given the complexity and potential for high recurrence of such tumors, early and accurate diagnosis is critical (9). A multidisciplinary diagnostic and treatment strategy, including thorough clinical evaluation, imaging studies, pathological analysis, and necessary genetic testing, plays a key role in managing these rare tumors (10). Through detailed case reporting and analysis, we aim to provide a more comprehensive understanding and reference for the diagnosis and treatment of such rare cases.

2 Case report

A 19-year-old Chinese female college student was found to have an abnormal chest lesion during a routine chest X-ray at university entry in August 2024 (Figure 1C). Further chest CT examination revealed bone destruction of the left 6th rib, accompanied by a soft tissue mass measuring approximately 68×119×93 mm. The lesion showed expansive and osteolytic changes, with ill-defined borders and patchy and arc-like calcifications, along with multiple septations. Enhanced CT images demonstrated heterogeneous enhancement of the mass, with destruction of the left 6th rib and adjacent soft tissue involvement (Figures 1A, B). The patient had no symptoms of chest pain, hemoptysis, dyspnea, fever, fatigue, or weight loss.

Figure 1

Physical examination revealed a well-oriented patient with stable vital signs and normal BMI. No palpable masses or lymphadenopathy were noted, and the respiratory, cardiovascular, and neurological systems showed no abnormalities.

Chest MRI further confirmed extensive bone destruction of the left 6th rib, along with a soft tissue mass measuring 116×67×102 mm. T1-weighted imaging showed slightly low signal intensity, while T2 fat-suppressed imaging displayed heterogeneous high signals. Coronal MRI images revealed cystic degeneration and necrosis within the mass, compressing adjacent structures such as the left lung and diaphragm (Figures 2A–C). Diffusion-weighted imaging (DWI) demonstrated areas of high signal intensity, and the apparent diffusion coefficient (ADC) map indicated decreased signal intensity, suggesting cystic changes and necrosis within the tumor.

Figure 2

On August 28, 2024, the patient underwent partial rib resection under general anesthesia at Lanzhou University Second Hospital. The resected tumor measured 14 × 10 × 7 cm, with a multiloculated cystic cut surface. Postoperative pathology revealed the tumor comprised spindle-shaped neoplastic cells and osteoclast-like giant cells, with significant cellular atypia and active mitoses (10/10 high-power fields), along with focal osteogenesis and cystic changes. Pathological examination confirmed the diagnosis of a malignant giant cell tumor (GCT) of the left 6th rib with chondrosarcomatous differentiation. Pathological sections demonstrated tumor tissues with prominent cellular atypia, cystic degeneration, and necrosis (Figures 3A–C). Immunohistochemistry results showed positivity for Vimentin, SMA, S-100, SATB2, Desmin, CD68, and CD163, while H3.3G34W, H3K36M, and CK were negative. The Ki-67 index ranged from 5% to 15%, indicating relatively high proliferative activity.

Figure 3

To confirm the diagnosis, the patient sought pathology consultation at Beijing Jishuitan Hospital on September 13 and at the First Medical Center of the PLA General Hospital on September 24. Both hospitals supported the diagnosis of malignant GCT with chondrosarcomatous differentiation. Immunohistochemical results at Jishuitan were consistent with those from Lanzhou University Second Hospital, while the PLA General Hospital showed positivity for H3.3G34W, p63, CD163, Vimentin, Desmin, and SMA, with a Ki-67 index of 25%.

The patient did not receive postoperative chemotherapy or radiotherapy. Follow-up evaluations began in October 2024, two months post-surgery, including imaging and physical examinations, which revealed no signs of recurrence. The patient recovered well without noticeable abnormalities and resumed her studies. A comprehensive follow-up strategy was developed, including imaging evaluations (CT or MRI) every three months to detect local recurrence or distant metastases. Monitoring tumor biomarkers was also included to assess disease progression and recurrence risks.

To provide further context for this rare case, Table 1 summarizes previously reported cases of Giant Cell Tumor (GCT) of the rib in adolescents. The table details patient demographics, clinical presentations, tumor characteristics, surgical approaches, pathological findings, and outcomes. This comparative summary highlights the variability in the presentation and management of rib GCTs, emphasizing the rarity of such cases and the necessity of individualized diagnostic and therapeutic strategies. A timeline summarizing key events, including diagnosis, treatment, and follow-up milestones, is presented in Figure 4 to provide a clear chronological overview of the patient’s clinical course.

Table 1

CaseAuthor & YearAge (years)SexSign & SymptomsSide and Location of GCTSize (cm)Surgery ApproachPathologyOutcome
1Locher GW et al., 197514MPainR, 6th rib, lateral arcNAEn-bloc resectionGCT - ABCNED, 3 years
2Locher GW et al., 197513.5MPain, massL, 8th rib, posterior arcNAEn-bloc resectionGCT - ABCNED, 5 years, scoliosis
3Locher GW et al., 19754.5FNo symptomsR, 4th rib, posterior arcNAEn-bloc resection*GCT - ABCNED, 1 year
4Athanasiadou F et al., 20037FMassR, lower rib, posterior arc8×4×4Needle biopsy + En-bloc resectionGCTNED, 1 year
5Özyüksel G et al., 202012FPain, massL, 7th rib, anterior arc7×10×10Tru-cut biopsy + En-bloc resectionGCTNED, 14 months
6Gui LS et al., 200921MPainRight, 9th rib6×8×8Tumor resection, bone cement fillingGCT - ABCNo recurrence, discharged
7Huang Y et al., 201515MPainLeft, 8th ribNACurettage and bone graftingGCTLow recurrence rate (<12.9%)

Summary of reported cases of Giant Cell Tumor (GCT) of the rib in adolescents.

M, male; F, female; NA, not available; R, right; L, left; *En-bloc resection for recurrent tumor previously underwent incomplete resection at another center, GCT, giant cell tumor; ABC, aneurysmal bone cyst; NED, no evidence of disease.

Figure 4

3 Discussion

This case of chondrosarcoma-like malignant giant cell tumor of the rib in an adolescent is representative of a highly aggressive bone tumor. Its rare location, occurrence in an adolescent, and chondrosarcomatous differentiation make both diagnosis and treatment extremely challenging. Multidisciplinary collaboration, particularly through a combination of imaging, pathology, and immunohistochemistry, helps improve diagnostic accuracy.

Chondrosarcomatous differentiation in GCT is rare and may involve complex cellular proliferation and tumor heterogeneity (11–13). Recent studies suggest that GCT formation may be associated with H3F3A gene mutations, which alter histone H3.3 function and affect cellular proliferation and differentiation (14, 15). H3F3A mutations are common in GCT patients, and identifying these mutations through genetic testing could not only reveal the tumor’s genetic characteristics but also provide scientific guidance for prognosis assessment and treatment strategy (14, 16). Additionally, abnormal expression of tumor suppressor genes like TP53, RB1, and MDM2 may play a role in malignant transformation during chondrosarcomatous differentiation, promoting tumor cell proliferation, inhibiting apoptosis, and increasing heterogeneity, thereby enhancing aggressiveness and recurrence risk (17).

Complete surgical resection remains the preferred treatment for chondrosarcoma-like malignant GCTs (18, 19). Despite successful resection, the tumor’s anatomical location and aggressive nature present technical challenges during surgery (15). If the tumor cannot be fully resected, radiotherapy or chemotherapy may be necessary to control tumor spread (18). With advances in molecular biology, targeted therapies for specific gene mutations, such as H3F3A or TP53, may improve patient outcomes in the future (14, 20). Recent studies suggest that combining bone-targeted therapies with tyrosine kinase inhibitors could provide novel therapeutic options for aggressive giant cell tumors, addressing both recurrence risks and tumor progression (21). These advancements highlight the importance of combining precise surgical techniques with emerging therapeutic strategies to address the aggressive behavior and recurrence potential of such tumors.

Although this patient showed no signs of recurrence within two months postoperatively, long-term monitoring remains crucial for managing these highly aggressive tumors (22). Regular follow-up should include periodic imaging studies, such as chest CT or MRI, to detect potential recurrence at the earliest stages (23, 24). Additionally, monitoring tumor biomarkers may provide supplementary information for assessing disease progression and recurrence risks (25). Given the high recurrence potential of chondrosarcoma-like malignant giant cell tumors, especially those with chondrosarcomatous differentiation, close surveillance is necessary to guide timely interventions and optimize long-term outcomes (26). A comprehensive follow-up strategy will be critical to ensure this patient’s continued recovery and to improve prognostic management for similar cases (27).

4 Conclusion

This case highlights the diagnostic and therapeutic challenges of managing chondrosarcoma-like malignant giant cell tumors of the rib in adolescents. The successful outcome through surgical treatment emphasizes the importance of multidisciplinary collaboration and individualized approaches for such rare tumors. Long-term follow-up remains essential to monitor recurrence risks and improve patient outcomes.

Statements

Data availability statement

The original contributions presented in the study are included in the article/supplementary material. Further inquiries can be directed to the corresponding author/s.

Ethics statement

Written informed consent was obtained from the individual(s) for the publication of any potentially identifiable images or data included in this article.

Author contributions

ZQ: Writing – original draft. LL: Conceptualization, Writing – original draft. TJ: Conceptualization, Writing – review & editing. CW: Writing – review & editing.

Funding

The author(s) declare that no financial support was received for the research, authorship, and/or publication of this article.

Conflict of interest

The authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

Generative AI statement

The author(s) declare that no Generative AI was used in the creation of this manuscript.

Publisher’s note

All claims expressed in this article are solely those of the authors and do not necessarily represent those of their affiliated organizations, or those of the publisher, the editors and the reviewers. Any product that may be evaluated in this article, or claim that may be made by its manufacturer, is not guaranteed or endorsed by the publisher.

References

  • 1

    Tobacco smoke and involuntary smoking. IARC Monogr Eval Carcinog Risks Hum. (2004) 83:1–1438.

  • 2

    DahlinDCCuppsREJohnsonEWJr.Giant-cell tumor: a study of 195 cases. Cancer. (1970) 25:1061–70. doi: 10.1002/1097-0142(197005)25:5<1061::aid-cncr2820250509>3.0.co;2-e

  • 3

    SchajowiczF. Giant-cell tumor (Osteoclastoma). In: Tumors and Tumorlike Lesions of Bone and Joints. Springer US, New York, NY (1981). p. 205–42.

  • 4

    Organization WH. WHO classification of tumours. In soft tissue and bone. 5th ed ed. Lyon, France: IARC Press (2020). p. 368.

  • 5

    SchmoldersJKoobSSchepersPet al. Lower limb reconstruction in tumor patients using modular silver-coated megaprostheses with regard to perimegaprosthetic joint infection: a case series, including 100 patients and review of the literature. Arch Orthopaedic Trauma Surg. (2017) 137:149–53. doi: 10.1007/s00402-016-2584-8

  • 6

    PicciP. Osteosarcoma (Osteogenic sarcoma). Orphanet J Rare Dis. (2007) 2:6. doi: 10.1186/1750-1172-2-6

  • 7

    MatsumineA. Endoprosthetic reconstruction for extremity osteosarcoma. In: UedaTKawaiA, editors. Osteosarcoma. Springer Japan, Tokyo (2016). p. 109–24.

  • 8

    TraubFAndreouDNiethardMet al. Biological reconstruction following the resection of Malignant bone tumors of the pelvis. Sarcoma. (2013) 2013:745360. doi: 10.1155/2013/745360

  • 9

    DaviesAMVanelD. Musculoskeletal tumors. In: DaviesAMPetterssonH, editors. Orthopedic Imaging: Techniques and Applications. Springer Berlin Heidelberg, Berlin, Heidelberg (1998). p. 359–78.

  • 10

    BalkeMAhrensHStreitbürgerAet al. Modular endoprosthetic reconstruction in Malignant bone tumors: indications and limits. In: TunnP-U, editor. Treatment of Bone and Soft Tissue Sarcomas. Springer Berlin Heidelberg, Berlin, Heidelberg (2009). p. 39–50.

  • 11

    ZhangLAbroBCampbellAet al. TP53 mutations in myeloid neoplasms: implications for accurate laboratory detection, diagnosis, and treatment. Lab Med. (2024) 55:686–99. doi: 10.1093/labmed/lmae048

  • 12

    Basu MallickAChawlaSP. Giant cell tumor of bone: an update. Curr Oncol Rep. (2021) 23:51. doi: 10.1007/s11912-021-01047-5

  • 13

    KoelscheCSchrimpfDTharunLet al. Histone 3.3 hotspot mutations in conventional osteosarcomas: a comprehensive clinical and molecular characterization of six H3F3A mutated cases. Clin Sarcoma Res. (2017) 7:9. doi: 10.1186/s13569-017-0075-5

  • 14

    BehjatiSTarpeyPSPresneauNet al. Distinct H3F3A and H3F3B driver mutations define chondroblastoma and giant cell tumor of bone. Nat Genet. (2013) 45:1479–82. doi: 10.1038/ng.2814

  • 15

    ChakarunCJForresterDMGottsegenCJet al. Giant cell tumor of bone: review, mimics, and new developments in treatment. Radiographics. (2013) 33:197–211. doi: 10.1148/rg.331125089

  • 16

    Luengo-AlonsoGMellado-RomeroMShemeshSet al. Denosumab treatment for giant-cell tumor of bone: a systematic review of the literature. Arch Orthopaedic Trauma Surg. (2019) 139:1339–49. doi: 10.1007/s00402-019-03167-x

  • 17

    BorkowskaAMSzumera-CiećkiewiczASzostakowskiBet al. Denosumab in giant cell tumor of bone: multidisciplinary medical management based on pathophysiological mechanisms and real-world evidence. Cancers. (2022) 14:2290. doi: 10.3390/cancers14092290

  • 18

    SkubitzKM. Giant cell tumor of bone: current treatment options. Curr Treat Options Oncol. (2014) 15:507–18. doi: 10.1007/s11864-014-0289-1

  • 19

    BalkeMSchremperLGebertCet al. Giant cell tumor of bone: treatment and outcome of 214 cases. J Cancer Res Clin Oncol. (2008) 134:969–78. doi: 10.1007/s00432-008-0370-x

  • 20

    AliNMNiadaSBriniATet al. Genomic and transcriptomic characterisation of undifferentiated pleomorphic sarcoma of bone. J Pathol. (2019) 247:166–76. doi: 10.1002/path.5176

  • 21

    De VitaAVanniSMiserocchiGet al. A rationale for the activity of bone target therapy and tyrosine kinase inhibitor combination in giant cell tumor of bone and desmoplastic fibroma: translational evidences. Biomedicines. (2022) 10:20220203. doi: 10.3390/biomedicines10020372

  • 22

    SpierenburgGGrimisonPChevreauCet al. Long-term follow-up of nilotinib in patients with advanced tenosynovial giant cell tumours: Long-term follow-up of nilotinib in TGCT. Eur J Cancer. (2022) 173:219–28. doi: 10.1016/j.ejca.2022.06.028

  • 23

    ChenCCLiauCTChangCHet al. Giant cell tumors of the bone with pulmonary metastasis. Orthopedics. (2016) 39:e68–73. doi: 10.3928/01477447-20151228-04

  • 24

    LiSLKongYGZouYet al. Giant cell tumor and giant cell reparative granuloma of bone of the head: CT and MR imaging findings. Comb Chem High Throughput Screen. (2023) 26:1180–5. doi: 10.2174/1386207325666220818124912

  • 25

    NohBJParkYK. Giant cell tumor of bone: updated molecular pathogenesis and tumor biology. Hum Pathol. (2018) 81:1–8. doi: 10.1016/j.humpath.2018.06.017

  • 26

    GitelisSWangJWQuastMet al. Recurrence of a giant-cell tumor with Malignant transformation to a fibrosarcoma twenty-five years after primary treatment. A Case Rep J Bone Joint Surg Am. (1989) 71:757–61. doi: 10.2106/00004623-198971050-00019

  • 27

    MaiZXieJLengCet al. An optimized postsurgery follow-up strategy for patients with esophageal cancer: a cohort study. Int J Surg. (2024) 110:332–41. doi: 10.1097/js9.0000000000000827

Summary

Keywords

case report, giant cell tumors, malignant, rib, chondrosarcoma-like

Citation

Qin Z, Li L, Jing T and Wang C (2025) Case report: A rare case of chondrosarcoma-like malignant giant cell tumor in adolescent rib: diagnostic challenges and treatment. Front. Oncol. 14:1523104. doi: 10.3389/fonc.2024.1523104

Received

05 November 2024

Accepted

24 December 2024

Published

15 January 2025

Volume

14 - 2024

Edited by

James Cm Ho, The University of Hong Kong, Hong Kong SAR, China

Reviewed by

Alessandro De Vita, Scientific Institute of Romagna for the Study and Treatment of Tumors (IRCCS), Italy

Wang Chun Kwok, The University of Hong Kong, Hong Kong SAR, China

Updates

Copyright

*Correspondence: Cheng Wang,

†These authors have contributed equally to this work and share first authorship

Disclaimer

All claims expressed in this article are solely those of the authors and do not necessarily represent those of their affiliated organizations, or those of the publisher, the editors and the reviewers. Any product that may be evaluated in this article or claim that may be made by its manufacturer is not guaranteed or endorsed by the publisher.

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